Temporal bone involvement of IgG4-related disease: A rare condition misleading to petrous apicitis causing lateral rectus palsy

© 2019 BMJ Publishing Group Limited. No commercial re-use. See rights and permissions. Published by BMJ. IgG4-related disease (IgG4-RD) of temporal bone is rare and clinical manifestation mimics infection. A 19-year-old female presented with progressive left earache and intermittent left nasal obstr...

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Main Authors: Sanathorn Chowsilpa, Sayanan Chowsilpa, Tanyathorn Teeranoraseth, Kannika Roongrotwattanasiri
Format: Journal
Published: 2019
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http://cmuir.cmu.ac.th/jspui/handle/6653943832/63705
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Institution: Chiang Mai University
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spelling th-cmuir.6653943832-637052019-03-18T02:24:25Z Temporal bone involvement of IgG4-related disease: A rare condition misleading to petrous apicitis causing lateral rectus palsy Sanathorn Chowsilpa Sayanan Chowsilpa Tanyathorn Teeranoraseth Kannika Roongrotwattanasiri Medicine © 2019 BMJ Publishing Group Limited. No commercial re-use. See rights and permissions. Published by BMJ. IgG4-related disease (IgG4-RD) of temporal bone is rare and clinical manifestation mimics infection. A 19-year-old female presented with progressive left earache and intermittent left nasal obstruction. Then, she rapidly developed left lateral rectus palsy. The physical examination revealed mild redness of left tympanic membrane and a small nasal polyp from the left middle meatus. CT scan showed left petrous apicitis and enhancing sinonasal mucosa. Therefore, Gradenigo's syndrome was first considered. The empirical intravenous antibiotic was immediately prescribed and surgery was performed. The intraoperative pale soft tissue mass in middle ear and polyp in the left nasal cavity were sent for pathological examination and found positive immunohistochemical stains for IgG4 in plasma cells. Systemic corticosteroid, the first-line treatment, was started and her symptoms were finally recovery. 2019-03-18T02:24:25Z 2019-03-18T02:24:25Z 2019-02-01 Journal 1757790X 2-s2.0-85062478857 10.1136/bcr-2018-228550 https://www.scopus.com/inward/record.uri?partnerID=HzOxMe3b&scp=85062478857&origin=inward http://cmuir.cmu.ac.th/jspui/handle/6653943832/63705
institution Chiang Mai University
building Chiang Mai University Library
country Thailand
collection CMU Intellectual Repository
topic Medicine
spellingShingle Medicine
Sanathorn Chowsilpa
Sayanan Chowsilpa
Tanyathorn Teeranoraseth
Kannika Roongrotwattanasiri
Temporal bone involvement of IgG4-related disease: A rare condition misleading to petrous apicitis causing lateral rectus palsy
description © 2019 BMJ Publishing Group Limited. No commercial re-use. See rights and permissions. Published by BMJ. IgG4-related disease (IgG4-RD) of temporal bone is rare and clinical manifestation mimics infection. A 19-year-old female presented with progressive left earache and intermittent left nasal obstruction. Then, she rapidly developed left lateral rectus palsy. The physical examination revealed mild redness of left tympanic membrane and a small nasal polyp from the left middle meatus. CT scan showed left petrous apicitis and enhancing sinonasal mucosa. Therefore, Gradenigo's syndrome was first considered. The empirical intravenous antibiotic was immediately prescribed and surgery was performed. The intraoperative pale soft tissue mass in middle ear and polyp in the left nasal cavity were sent for pathological examination and found positive immunohistochemical stains for IgG4 in plasma cells. Systemic corticosteroid, the first-line treatment, was started and her symptoms were finally recovery.
format Journal
author Sanathorn Chowsilpa
Sayanan Chowsilpa
Tanyathorn Teeranoraseth
Kannika Roongrotwattanasiri
author_facet Sanathorn Chowsilpa
Sayanan Chowsilpa
Tanyathorn Teeranoraseth
Kannika Roongrotwattanasiri
author_sort Sanathorn Chowsilpa
title Temporal bone involvement of IgG4-related disease: A rare condition misleading to petrous apicitis causing lateral rectus palsy
title_short Temporal bone involvement of IgG4-related disease: A rare condition misleading to petrous apicitis causing lateral rectus palsy
title_full Temporal bone involvement of IgG4-related disease: A rare condition misleading to petrous apicitis causing lateral rectus palsy
title_fullStr Temporal bone involvement of IgG4-related disease: A rare condition misleading to petrous apicitis causing lateral rectus palsy
title_full_unstemmed Temporal bone involvement of IgG4-related disease: A rare condition misleading to petrous apicitis causing lateral rectus palsy
title_sort temporal bone involvement of igg4-related disease: a rare condition misleading to petrous apicitis causing lateral rectus palsy
publishDate 2019
url https://www.scopus.com/inward/record.uri?partnerID=HzOxMe3b&scp=85062478857&origin=inward
http://cmuir.cmu.ac.th/jspui/handle/6653943832/63705
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